Linkage of Niemann-Pick disease type C to human chromosome 18.

نویسندگان

  • E D Carstea
  • M H Polymeropoulos
  • C C Parker
  • S D Detera-Wadleigh
  • R R O'Neill
  • M C Patterson
  • E Goldin
  • H Xiao
  • R E Straub
  • M T Vanier
چکیده

We analyzed the involvement of chromosome 18 in Niemann-Pick disease type C (NPC), an autosomal recessive cholesterol-processing disorder. Within affected offspring, the chromosome 18 parental contributions were identified by using allele-specific microsatellite markers. Significant linkage of NPC to an 18p genomic marker, D18S40, was indicated by a two-point lod score of 3.84. Analysis of meiotic chromosomal breakpoint patterns among the affected individuals indicated that the NPC gene is pericentromerically localized on human chromosome 18.

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عنوان ژورنال:
  • Proceedings of the National Academy of Sciences of the United States of America

دوره 90 5  شماره 

صفحات  -

تاریخ انتشار 1993